Pressure alopecia is a kind of localized hair loss, resulting from excessive or chronic local pressure of the scalp. It is usually described in patients with immobilization of the head during longstanding surgery or in bed-ridden state; however, it can rarely occur from a long-term use of various fixation instruments including head straps, orthodontic headgears, hairpins, and even wigs. A 9-year-old female presented with a localized hair loss patch on the frontal scalp after putting on a headgear appliance for several days due to her orthodontic treatment. She was complaining of pruritus, bruising and oozing on the area where direct pressure was applied by the headgear. Physical examination showed a 3.5 x 3.5 cm, round bald patch and another 2.0 x 3.0 cm, oval bald patch on the frontal scalp. Dermoscopy revealed scattered yellow and black dots with some broken hairs and without any exclamation mark hairs, which is the characteristics of alopecia areata. Histopathologic findings revealed trichomalacia with pigmented cast, and increased number of catagen and telogen hair follicles, but with no peribulbar infiltration. Based on clinical and histologic findings, he was diagnosed as pressure alopecia due to orthodontic headgear. After 3 weeks of removal of the headgear, newly emerging hairs was observed on the lesion. During the 4 months of follow-up period, complete hair regrowth was noted.